Ameloblastoma is a benign odontogenic neoplasm that frequently affects the mandible. The term ameloblastoma includes several clinical, radiological, and histological types. In many cases, it poses significant diagnostic and therapeutic challenges. Ameloblastoma is a benign tumor that invades locally with the most common site being the third molar region mandibular jaw. Most commonly ameloblastoma occurs in the mandibular third molar region up to 66%, followed by 11% in the mandibular premolar region, 10% in the mandibular anterior region, 6% in the maxillary anterior, and posterior region, and only 1% in the maxillary premolar region. Here we present a rare case of Unicystic ameloblastoma occurring in the anterior mandibular region crossing the midline in a 17-year-old-male.
